TY - JOUR
T1 - A Solitary Intestinal Myofibroma
T2 - A Rare Cause of Neonatal Anemia
AU - Ottenhoff, Janna S.E.
AU - Nikkels, Peter G.J.
AU - Terwisscha van Scheltinga, C. E.J.
AU - Naeije, L.
N1 - Publisher Copyright:
© 2017 The Author(s).
PY - 2017/12/28
Y1 - 2017/12/28
N2 - Solitary infantile myofibroma with visceral involvement is very rare. We present an unusual case of a solitary myofibroma with abdominal localization in a 1-day-old female neonate who presented with severe anemia and rectal bleeding. A bleeding myofibroma was found, located in the wall of the jejunum, and totally resected. In case of a solitary lesion, treatment is relatively easy and effective, with excellent prognosis after total resection. The multiple form (myofibromatosis) has a poor prognosis with low survival rates. We therefore recommend total body MRI for all patients diagnosed with myofibroma to rule out other lesions.
AB - Solitary infantile myofibroma with visceral involvement is very rare. We present an unusual case of a solitary myofibroma with abdominal localization in a 1-day-old female neonate who presented with severe anemia and rectal bleeding. A bleeding myofibroma was found, located in the wall of the jejunum, and totally resected. In case of a solitary lesion, treatment is relatively easy and effective, with excellent prognosis after total resection. The multiple form (myofibromatosis) has a poor prognosis with low survival rates. We therefore recommend total body MRI for all patients diagnosed with myofibroma to rule out other lesions.
KW - Gastrointestinal surgery
KW - Intestinal obstruction
KW - Myofibroma
KW - Neonatal anemia
UR - http://www.scopus.com/inward/record.url?scp=85031785583&partnerID=8YFLogxK
U2 - 10.1159/000481305
DO - 10.1159/000481305
M3 - Article
C2 - 29279689
AN - SCOPUS:85031785583
VL - 10
SP - 890
EP - 896
JO - Case Reports in Oncology
JF - Case Reports in Oncology
IS - 3
ER -